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GA4GH Connect 2026 Workshop Resources

This page brings together the ALS TDI resources for the April 16 workshop at GA4GH Connect in Montreal and materials related to accessing ALS TDI data.


Accessing ALS TDI data through ARC Data Commons

Academic and nonprofit researchers can access ARC Data Commons resources at no cost with a Data Use Agreement.

Request access to ARC Data Commons


How to cite ARC data

ALS Therapy Development Institute (ALS TDI). (2023). ALS Research Collaborative (ARC) [Data set]. Amyotrophic Lateral Sclerosis Therapy Development Institute. https://doi.org/10.71944/C3NA-9124


Preprint

For additional background on the ALS TDI ARC Natural History Study ARC data resource, see our preprint:

Boyce et al. — The ALS Research Collaborative: A Long Running Multimodal ALS Natural History Resource


Search the ALS TDI data dictionary

Use the search box below to filter variables in the uploaded data dictionary. Note that this contains select surveys only: please see preprint above for a comprehensive overview of the ARC data.

Sheet Name Variable Name Data Type
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Prototype patient narrative

Below is a prototype synthetic participant narrative.

Participant Summary

Participant ID: 123
Snapshot Date: 2026-04-08
Cohort: ALS Natural History
Demographics: 72-year-old male, New York, USA

Participant voice

“My hands weakened first, but my speech hasn’t changed much.”

“I’ve slowed down a lot over the years, especially with physical work.”

“Breathing feels okay most days, but I get tired faster.”

1. Clinical Identity

Primary Diagnosis: Amyotrophic Lateral Sclerosis (Definitive)

  • Onset: Age 57, right hand
  • Disease course: Slowly progressive

Genetic findings - GENE1 - GENE2 - ETC - Clinical significance not established

Study context - ALSTDI0103 — Imaging & Biofluid Biomarkers - Qualified participant

2. Phenotypic Profile

Motor system

  • Progressive limb weakness (HPO: HP:0001324)
  • Declining functional mobility, with ALSFRS and accelerometry showing concordant decline
  • Muscle cramping (HP:0003394)

Bulbar function

  • Clinically reported dysarthria and dysphagia (HP:0001260, HP:0002015)
  • Instrumented voice metrics remain stable, suggesting a discordant signal

Respiratory

  • Chronic respiratory insufficiency (HP:0002093)
  • Stable functional respiratory scores

Neurobehavioral

  • Pseudobulbar affect (HP:0000746)

Other

  • Sialorrhea (HP:0002307)
  • Peripheral neuropathy (HP:0009830)

3. Longitudinal Disease Trajectory

Functional decline (ALSFRS-R)

  • 132 observations from 2015 to 2026
  • Total score declined from 25 to approximately 14
  • Estimated slope: -0.06 per month, consistent with slow progression

Subdomains - Motor: steady decline - Bulbar: stable - Respiratory: stable

Passive activity (accelerometry)

  • 124 observations
  • Activity level declined from approximately 615 to approximately 236 units
  • Pattern consistent with bilateral upper limb decline

Voice biomarkers

  • 89 observations
  • Mean stability around 0.85, with a wide range
  • Interpretation: relative preservation of bulbar motor control

4. Multimodal Concordance Summary

Domain Signal Source Interpretation
Motor ALSFRS ↓ + activity ↓ Progressive decline
Bulbar Voice stable vs. EHR symptoms Partial discordance
Respiratory ALSFRS stable + EHR positive Early or stable impairment
Behavior EHR (PBA) only Underreported in survey

5. Participant-Reported Context

Lifestyle / exposure

  • Former light smoker, approximately 30 years
  • Farm or ranch environment
  • Construction / foreman occupation

Medical history

  • Prior head injuries with loss of consciousness
  • Falls
  • Allergies

Family history

  • Cancer, including bone and kidney cancer

6. EHR Validation Layer

Diagnosis concordance

  • ALS confirmed (ICD-10: G12.21)
  • Supporting conditions include:
  • dysarthria
  • dysphagia
  • respiratory insufficiency
  • pseudobulbar affect
  • sialorrhea
  • cramping

Medication alignment

Therapeutic Area Survey Report EHR Record Concordance
ALS Riluzole Riluzole
Motor Gabapentin, Tizanidine Same
Bulbar/PBA Nuedexta DM/Q
Other Lansoprazole, Tamsulosin Same
Supplements Vitamins D/C/E Partial ~

Additional EHR-only medications are present for supportive and symptomatic care.

Healthcare utilization

  • MRI brain
  • Chest X-ray
  • CT abdomen
  • Echocardiogram
  • Sleep study
  • Vascular ultrasound

7. Laboratory Snapshot

Recent labs (Feb 2026)

  • Hemoglobin: 13.9
  • Hematocrit: 40.5
  • WBC: 7.8
  • Sodium: 135
  • Glucose: 72

No major laboratory abnormalities appear to be driving the phenotype.

8. Integrated Interpretation

This participant demonstrates a slowly progressive ALS phenotype characterized by:

  • consistent motor decline across functional and passive measures
  • preserved bulbar function in digital voice metrics
  • stable respiratory function with early EHR evidence of impairment

EHR data strongly corroborates diagnosis, symptom spectrum, and treatment patterns.

Key insight:
There is a cross-modal discordance between: - stable voice biomarkers - clinically coded bulbar symptoms

This may suggest early or subclinical bulbar involvement, or differences in measurement sensitivity.

9. Data Completeness / Provenance

Modality Coverage
ALSFRS-R 132
Accelerometry 124
Voice 89
Surveys Extensive
EHR Longitudinal (ICD, RxNorm, LOINC, CPT)

10. Abstract

Disease: ALS (G12.21)
Onset: 57 years
Course: Slow progression

Core phenotypes - progressive limb weakness - dysarthria - dysphagia - respiratory insufficiency - pseudobulbar affect - muscle cramps - sialorrhea

Modifiers - preserved bulbar function by instrumented assessment - reduced activity on accelerometry

Evidence layers - participant-reported outcomes - digital biomarkers (ALSFRS, accelerometry, voice) - EHR diagnoses, medications, and procedures

11. One-Line Summary

Slow-progressing limb-onset ALS with multimodal-confirmed motor decline, preserved voice metrics, and strong EHR concordance, with mild cross-modal bulbar discordance.